Source: MONTANA STATE UNIVERSITY submitted to NRP
PATHOGENESIS OF HELICOBACTER SUIS INFECTION IN PIGS AND HUMANS
Sponsoring Institution
National Institute of Food and Agriculture
Project Status
COMPLETE
Funding Source
Reporting Frequency
Annual
Accession No.
1015768
Grant No.
(N/A)
Cumulative Award Amt.
(N/A)
Proposal No.
(N/A)
Multistate No.
(N/A)
Project Start Date
Jul 1, 2018
Project End Date
Jun 30, 2021
Grant Year
(N/A)
Program Code
[(N/A)]- (N/A)
Recipient Organization
MONTANA STATE UNIVERSITY
(N/A)
BOZEMAN,MT 59717
Performing Department
Microbiology & Immunology
Non Technical Summary
This study is focused on He/icobacter suis, a bacterial zoonotic pathogen that causes gastric inflammation in both humans and domestic pigs. Our preliminary data obtained by screening slaughterhouse samples from Big Timber, MT, revealed that a significant proportion of Montana pigs are infected with H. suis, and that infection is associated with gastric pathology, consistent with earlier studies. We here propose to analyze additional pig stomach tissue samples for the presence of infection and pathology in order to obtain reliable data on the prevalence of this infection. We will also perform ex vivo and in vitro analyses to characterize the inflammatory and immune response that H. suis causes in the pig and human stomach. These data will fill an important knowledge gap in our understanding of H. suis pathogenesis and will allow us to better estimate the risk of human H. suis transmission and disease.
Animal Health Component
0%
Research Effort Categories
Basic
100%
Applied
0%
Developmental
0%
Classification

Knowledge Area (KA)Subject of Investigation (SOI)Field of Science (FOS)Percent
31135991090100%
Knowledge Area
311 - Animal Diseases;

Subject Of Investigation
3599 - Swine, general/other;

Field Of Science
1090 - Immunology;
Goals / Objectives
H. suis infection is associated with gastric pathology in humans, pigs, and other domestic and laboratory animals. However, little is known about how H. suis bacteria interact with the host to cause inflammation and pathology. We hypothesize that H. suis causes gastric disease in pigs and humans by inducing pro-inflammatory responses in gastric epithelial cells. We will test our hypothesis by addressing thefollowing objectives:Objective 1: Determine the level of infection with H. suis in Montana pigs and elucidate the association of H. suis infection with gastric disease. To analyze whether H. suis causes gastric disease in Montana pigs, we will screen slaughterhouse samples of gastric body and antrum for the presence of H. suis infection and gastric pathology. Specifically, H. suis infection will be determined by quantitative PCR and rapid urease CLO test, and tissue sections from gastric antrum and the gastric body will be analyzed microscopically for inflammatory alterations and the presence of spiral-shaped bacteria. The presence of H. suis in select samples will be confirmed by microbial sequencing. We will also collect data on pig breeds, husbandry methods, and carcass weights for possible correlation with infection rates and pathology. These experiments will reveal the disease burden of H. suis gastritis in Montana pigs.Objective 2: Determine the mechanisms by which H. suis drivesepithelial inflammatory responses using a human gastric organoid model. The gastric epithelium is the first point of contact between Helicobacter bacteria and the host. In the infected human stomach, immune cells including neutrophils, macrophages and dendritic cells are attracted to the sites of infection by chemokines and cytokines released from the epithelium, in particular IL-8. In preliminary experiments, we showed that H. suis induced gastric epithelial IL-8 expression in human organoids, although H. suis lacks the Gag pathogenicity island that is the major driver of IL-8 secretion induced by H. pylori (Vermoote et al. 2011). Here, we will analyze the molecular mechanisms by which H. suis induces epithelial cell inflammation. We will use human gastric organoids to analyze (1) epithelial proinflammatory cytokine and chemokine production in response to H. suis, (2) NF-KB activation in response to H. suis, and (3) signaling pathways involved in NF-KB activation. Responses to H. suis will be compared to responses to H. pylori, the most common human gastric pathogen.Objective 3: Establish a porcine gastric organoid model to analyze the inflammatory epithelial cell response of porcine gastric epithelial cells to H. suis. A recent report has highlighted significant differences in the immune response to H. suis infection in different species (Bosschem et al. 2017).Therefore, we propose to compare the response of H. suis-infected porcine gastric epithelial cells to that of human gastric epithelial cells. Based on our experience with human gastric organoids, we will establish gastric organoid lines from the porcine stomach. As described for Objective 2 above, porcine gastric organoids will be infected with H. suis bacteria in vitro, and cytokine expression, NF-KB activation and induction of cell death will be determined.
Project Methods
Objective 1: Determine the level of infection with H. suis in Montana pigs and elucidate the association of H. suis infection with gastric disease.1.1. Analyze porcine gastric tissue samples for the presence of H. suis infection and gastric pathology. Porcine tissue samples for analysis of H. suis infection will be obtained from a commercial slaughter operation in Big Timber, MT. Data on carcass weight, farm of origin and husbandry system will be provided. We will analyze tissue collected from the pyloric antrum and the glandular part of the gastric body for H. suis infection by rapid urease CLO Test, and for H. suis urease-specific sequences by quantitative PCR. To confirm the specificity of the PCR detection, PCR products for H. suis urease genes from a subset of samples will be sequenced. In addition, paraffin-embedded sections obtained from gastric antrum and body will be analyzed for the presence of spiral bacteria and scored for histopathological changes. We have already collected samples from 100 pigs and will continue to analyze these samples and collect additional tissues until matched CLO-test, qPCR and histopathological analyses have been performed on 100 - 150 samples. Pearson's correlation coefficient will be calculated to determine a relationship between H. suis copy numbers and pathology scores. 1.2. Using immunofluorescence microscopy, characterize the cellular infiltrates induced by H.suis infection of the porcine stomach. H. pylori infection of the human stomach leads to chronic active gastritis with initial polymorphonuclear infiltrates and increased numbers of lymphocytic infiltrates and lymphoid follicles seen at later stages. In contrast, infiltrates associated with porcine H. suis infection have been characterized as mostly lymphocytic, with a large number of plasma cells present. However, these results were exclusively based on tissue staining with H&E. Here, we will analyze gastric tissue samples from H. suis-infected and non-infected pigs for mucosal infiltration with mononuclear phagocytes, T cells, B cells and neutrophilic granulocytes by immunocytochemistry, using antibodies to SLA-DQ, CD3, CD79a and SWC8, respectively. Antibody binding will be visualized using appropriate horse radish peroxidase-labeled secondary antibodies and DAB as a substrate. Slides will be analyzed on an Olympus BX60 upright fluorescence microscope, and cellular infiltrates will be quantified by digital image analysis.Objective 2: Determine the mechanisms by which H. suis drives epithelial inflammatory responses using a human gastric organoid model2.1. Determine whether H. suis induces NF-κB signaling in primary human gastric epithelial cells through the engagement of NOD1, TLR2 and/or CD74. To analyze the inflammatory response of primary human gastric epithelial cells to H. suis, we will use gastric organoid cultures derived from human tissue samples generated and maintained as described in our recent publication (Sebrell et al., 2018). We will infect the gastric organoids with H. suis DSM 19735T, or with H. pylori as a positive control. To infect epithelial cells, organoids will be re-seeded on collagen-coated plates to obtain confluent monolayers and bacterial will be added to the plates. We will then analyze NF-κB activation by microscopy to determine nuclear translocation and by phosflow FACS analysis to determine p65 phosphorylation. CagA-positive and CagA PAI-deficient H. pylori mutants will be used to determine the contribution of CagA signaling to H. pylori-induced NF-κB-activation. If we can show that H. suis activates NF-κB, we will next determine whether NOD1, TLR2 or CD74 are involved in the activation pathway. TLR2 and CD74 will be blocked using neutralizing antibodies, and NOD1 will be blocked using the small molecule inhibitor ML130. Cells will then be treated with H. suis or H. pylori and analyzed for NF-κB activation as described above. Having shown that H. suis drives IL-8 expression, we anticipate that H. suis infection also results in NF-κB phosphorylation and nuclear translocation.2.2. Determine whether H. suis induces gastric epithelial cell release of pro-inflammatory cytokines to initiate gastric inflammation. As shown in preliminary experiments, H. suis caused increased IL-8 gene expression in primary human gastric epithelia. To confirm that H. suis infection causes secretion of IL-8 and other pro-inflammatory cytokines, human gastric organoids will be re-seeded as monolayers on collagen-coated transwell inserts. The gastric epithelial cells will then be treated with live H. suis, H. suis lysates, live H. pylori, or will be left untreated. We will culture supernatants for cytokine secretion using a cytometric bead array. In parallel, cultured cells will be analyzed for H. suis-induced cell death using Annexin/PI. Morphological alterations of the epithelial cells will be monitored by microscopy. We hypothesize that H. suis and H. pylori infection will induce gene expression and secretion of IL-8 and other epithelial cell associated pro-inflammatory cytokines, particularly IL-1β and IL-6. However, since virulence factor expression differs between H. suis and H. pylori, we do anticipate to find differences in the magnitude of the response and the cytokine profile.Objective 3: Establish a porcine gastric organoid model to analyze the inflammatory epithelial cell response of porcine gastric epithelial cells to H. suis.3.1. Optimize the establishment and culture of porcine gastric organoids from antrum and gastric body. In our preliminary experiments, we were able to establish organoid cultures from porcine stomach using our human gastric organoid protocol. However, efficiency of spheroid formation and growth rates of the organoids were very low. Here, we seek to improve our protocol for porcine gastric organoid generation and maintenance. We will compare our published collagenase digestion protocol to gland isolation protocols that involve EDTA treatment alone and to a protocol that utilizes a commercially available dissociation reagent. Second, we will optimize our growth medium by varying medium concentrations of growth factors Wnt3a, R-spondin, ROCK inhibitor and the TGF-β inhibitor and supplementation of media with additional supplements such as epidermal growth factor and niacin that have been used by others to maintain optimal growth of gastric organoids. Organoid formation and growth under different conditions will be monitored by live imaging microscopy, and epithelial cell differentiation will be confirmed by RT-PCR analysis. We anticipate that by adjusting our gland isolation and organoid culture protocols, we will successfully establish multiple porcine gastric organoid lines for in vitro modeling of H. suis infection.3.2. Determine whether H. suis infection of porcine gastric organoids induces pro-inflammatory epithelial cell responses and epithelial cell death. To determine the epithelial response of the porcine gastric epithelium to H. suis, we will analyze porcine gastric organoids for NF-κB activation, pro-inflammatory cytokine expression and cell death. As described for Objective 2, Exp. 1, we will infect the porcine organoids with H. suis and analyze them for NF-κB activation. If we can successfully show that H. suis activates the pro-inflammatory transcription factor NF-κB in the porcine gastric epithelium, we will next analyze H. suis-induced proinflammatory cytokine expression using quantitative RT-PCR. If we can determine increased expression of any of the cytokines by qRT-PCR, we will confirm these data by performing ELISA analyses of culture supernatants. We will also analyze the infected porcine gastric organoid cells for epithelial cell death. These experiments will provide initial insights into the pro-inflammatory response of the porcine gastric epithelium to de novo H. suis infection.

Progress 10/01/19 to 09/30/20

Outputs
Target Audience:The target audience for our work is the scientific community that is focused on microbial pathogenesis in the gastrointestinal tract as well as graduate students and undergraduate students who are involved in our research and who are receiving research training. Changes/Problems:As stated in the previous report, we submitted grant proposals to the USDA and to the National PorkBoard to support research on Helicobacter suis and porcine organoids, buthave been unable to attract significant funding.Since the majority of the funded work in my laboratory is focused on H. pylori and human gastric organoids and epithelial cells, we will continue toperform our experimentsin these model systems. What opportunities for training and professional development has the project provided?This project has provided training opportunities related to organoid work fortwo graduate students and one undergraduate student in the past year. How have the results been disseminated to communities of interest?Results have been disseminated through peer-reviewed publications and an invitedpresentation by Dr. Bimczok at Vanderbilt University in October 2019. Talks and poster presentations about our organoid data at several 2020 conferences (Digestive Diseases Week, American Association of Immunologists Meeting, James W. Freston Single Topic Conference on Gastrointestinal Organoids and Engineered Organ Systems) were cancelled because of COVID-19. What do you plan to do during the next reporting period to accomplish the goals?In the next reporting period, we will continue our work on human Helicobacter pylori infection in both organoids and patient tissues. Using our organ-on-a chip model, we will further analyze the impact that the H. pylori-infected gastric epithelium has on immune cells in the mucosa. We anticipate that we will publish a manuscript on the image analysis application within the next year.

Impacts
What was accomplished under these goals? We have continued to focus on investigating human gastric organoids as a model for Helicobacter pylori infection, due to the lack of funding for investigating H. suis infection in a porcine organoid model.In human gastric organoids, active H. pylori infection could routinely be maintained for 10 days.Extending our previous co-culture data where we showed that epithelial chemokines such as IL-8relased by H. pylori-infected organoids cause recruitment of monocyte-derived dendritic cells (Sebrell et al. 2019), we recentlydemonstrated that autologous, primarygastric mucosal dendritic cells likewise show migration towards the organoid epithelium.We also showed thatH. pylori infected organoids that were co-cultured with monocyte-derived dendritic cells induced increased activation and maturation of the dendritic cells. Through an NIH-funded project, we are now using an organ-on-a-chip model to analyze gastric organoid interactions with H. pylori and dendritic cells in a highly controlled environment that enables confocal live imaging over multiple days. Importantly, we have collaborated with Dr. Zosso in the Department of Mathematical Sciences to develop an image analysis application that enables us to analyze dendritic cell recruitment to H. pylori-infected epithelial cells in human tissue sections. This application automatically recognizes dendritic cells in immunofluorescently labeled gastric tissue sections and measures the disstance between the dendritic cells and the gastric epithelium as a proxy for dendritic cell recruitment.Through Monte Carlo modeling, we can also determine whether observed dendritic cell-epithelial cell distances are statistically different from random cell distribution.We are currently in the process of analyzing tissues from 8-10 human subjects with either active H. pyori infection or without H. pylori infection for their DC distribution.

Publications

  • Type: Journal Articles Status: Published Year Published: 2020 Citation: Roe MM, Hashimi M, Swain S, Woo KM, Bimczok D. p38 MAPK signaling mediates retinoic acid-induced CD103 expression in human dendritic cells. Immunology. 2020 Nov;161(3):230-244. doi: 10.1111/imm.13246. Epub 2020 Sep 14. PMID: 32737889
  • Type: Journal Articles Status: Published Year Published: 2020 Citation: Sayed IM, Sahan AZ, Venkova T, Chakraborty A, Mukhopadhyay D, Bimczok D, Beswick EJ, Reyes VE, Pinchuk I, Sahoo D, Ghosh P, Hazra TK, Das S. Helicobacter pylori infection downregulates the DNA glycosylase NEIL2, resulting in increased genome damage and inflammation in gastric epithelial cells. J Biol Chem. 2020 Aug 7;295(32):11082-11098.
  • Type: Journal Articles Status: Published Year Published: 2020 Citation: Sierra JC, Piazuelo MB, Luis PB, Barry DP, Allaman MM, Asim M, Sebrell TA, Finley JL, Rose KL, Hill S, Holshouser SL, Casero RA, Cleveland JL, Woster PM, Schey KL, Bimczok D, Schneider C, Gobert AP, Wilson KT Spermine oxidase mediates Helicobacter pylori-induced gastric inflammation, DNA damage, and carcinogenic signaling. Oncogene 2020 May;39(22):4465-4474. doi: 10.1038/s41388-020-1304-6.
  • Type: Journal Articles Status: Published Year Published: 2020 Citation: Caston RR, Sierra JC, Foegeding NJ, Truelock MD, Campbell AM, Frick-Cheng AE, Bimczok D, Wilson KT, McClain MS, Cover TL. Functional Properties of Helicobacter pylori VacA Toxin m1 and m2 Variants. Infection and Immuninty. 2020 May 20;88(6):e00032-20. doi: 10.1128/IAI.00032-20.
  • Type: Journal Articles Status: Other Year Published: 2021 Citation: C. Goodman, K. Lyon, M. Roe, T.A. Sebrell, A. Moore, G. Bala, G. Stoner, D. Bimczok. Using a high-throughput assay to quantify antibacterial effects of black and red raspberries and blackberries in H. pylori infection. In preparation
  • Type: Journal Articles Status: Other Year Published: 2021 Citation: C. Potts, J. Schearer, D. Bain, R. Ayler, J. Love, D. Zosso, D. Bimczok. Application of spatial statistics to biomedical images for evaluation of mucosal epithelial cell-immune cell interactions. In preparation


Progress 10/01/18 to 09/30/19

Outputs
Target Audience:The target audience for our work is the scientific community that is focused on microbial pathogenesis in the gastrointestinal tract as well as graduate students and undergraduate students who are involved in our research and who are receiving research training. Changes/Problems:Since currently funded work in my laboratory is focused on Helicobacter pylori, and Helicobacter suis is extremely difficult to culture, we will be performing the majority of our future organoid experiments with H. pylori. What opportunities for training and professional development has the project provided?This project has provided training opportunities related to organoid work for one graduate student, one graduate rotation student and one undergraduate student in the past year. How have the results been disseminated to communities of interest?Results have been disseminated through peer-reviewed publications, an oral presentation at the Annual Meeting of the American Association of Immunologists (Hashimi) and through two invited seminar talks by Dr. Bimczok at Vanderbilt University and the University of Knoxville, Tennessee. What do you plan to do during the next reporting period to accomplish the goals? Nothing Reported

Impacts
What was accomplished under these goals? We have investigated inflammatory responses of human gastric organoids to Helicobacter infection and have shown that H. pylori infection induces the release of multiple chemokines, including CXCL1, CXCL16, CXCL17, and CCL20, from the gastric epithelium. These chemokines also were detected at increased levels in Helicobacter-infected gastric tissues. Dendritic cells co-cultured with Helicobacter-infected gastric organoids showed an increased chemotactic migration towards the gastric epithelium and were able to phagocytose luminal bacteria. There data were published earlier this year in Cellular and Molecular Gastroenterology and Hepatology (Sebrell et al. 2019). We also collaborated on a publication on colonic epithelial wound healingthat used human organoids (Swain et al 2019). To analyze gastric epithelial cell death in Helicobacter-infected organoids, we have generated a Caspase 3 reporter organoid line using lentiviral transfection with the ZipCasp3 plasmid. The apoptosis reporter organoids are currently undergoing experimental evaluations and will enable us to detect apoptotic events in live imaging experiments

Publications

  • Type: Journal Articles Status: Published Year Published: 2019 Citation: T.A. Sebrell, M. Hashimi, B. Sidar, R. Wilkinson, L. Kirpotina L, M.T. Quinn, Z. Malko�, P.J. Taylor, J.N. Wilking, D. Bimczok. Human gastric epithelial cells recruit DCs for luminal H. pylori uptake in a novel gastric epithelial spheroid co-culture model. Cellular and Molecular Gastroenterology and Hepatology 2019. S2352-345X(19)30026-8. doi: 10.1016/j.jcmgh.2019.02.010
  • Type: Journal Articles Status: Published Year Published: 2019 Citation: 30. S.D. Swain, H.N. Grifka-Walk, J. Gripentrog, M. Lehmann, B. Deuling, B. Jenkins, H. Liss, N. Blaseg, D. Bimczok, D.J. Kominsky. Slug and Snail have differential effects in directing colonic epithelial wound healing and partially mediate the restitutive effects of butyrate. American Journal of Physiology: Gastrointestinal and Liver Physiology. 2019. https://doi.org/10.1152/ajpgi.00071.2019.
  • Type: Book Chapters Status: Awaiting Publication Year Published: 2020 Citation: D. Bimczok, A. M�ller, P. D. Smith . Helicobacter pylori infection. In: P.D. Smith, R.S. Blumberg, T.T. MacDonald (eds.). Principles of Mucosal Immunology. 2nd Edition, Garland Science, New York, NY.


Progress 07/01/18 to 09/30/18

Outputs
Target Audience:Wesubmitted a USDA proposal related to this project in July of this year. Changes/Problems: Nothing Reported What opportunities for training and professional development has the project provided?Samples generated through this project have been used for demonstration purposes in the Veterinary Microscopic anatomy class (VM510) that I teach through the WIMU regionsl program in veterinary medicine. How have the results been disseminated to communities of interest?An application for additional funding for this project was submitted as a stregthening standard proposal to the USDA AFRI program in July of this year. What do you plan to do during the next reporting period to accomplish the goals?Objective 1: Determine the level of infection withH. suisin Montana pigs and elucidate the association ofH. suisinfection with gastric disease. As described above, we have already collected tissue samples from 104 pig stomachs for analysis of H. suis infection. Within the next year, we plan on completing our analysis of these samples for the presence of H. suis infection (quantitative PCR and CLO-Test) and pathological alterations (histopathological scoring of antral and fundic tissue sections). Objective 2: Determine the mechanisms by whichH. suisdrivesepithelial inflammatory responses using a human gastric organoid model. To elucidate the inflammatory response induced by H. suis in the gastric epithelium, we will perform additional organoid infection experiments and will analyze activation of the inflammatory transcription factor NF-kappaB and gene expression of inflammatory cytokines. and chemokines.

Impacts
What was accomplished under these goals? To analyze the prevalence of H. suis infection in Montana pigs, we have collected gastric tissue samples from >100 slaughter house pigs and have processed these samples for histopathology and PCR analysis. Preliminary data from our analyses showed that aproportion of the pigs was naturally infected with H. suis bacteria, and that the presence of H. suis urease correlated with increased gastric pathology. In in vitro experiments performed for Objective 2, we have infected primary human gastric epithelial cells cultured as organoids with H. suis. H. suis induced a similar increase in interleukin 8 gene expression in the gastric epithelium as H. pylori. To compare the response of the human gastric epithelium with that of the porcine epithelium, we also have started to generate gastric organoid lines from porcine stomach.

Publications